Uterus didelphys with cervical agenesis associated with adenomyosis, a leiomyoma and ovarian endometriosis. A case report.

Chih-Chun Yang, Jen-Yu Tseng, Pu Chen, Peng-Hui Wang, Peng‐Hui Wang
The Journal of reproductive medicine · 2002 · vol. 47(11) , pp. 936–8 · PMID:12497685 · W74918475
article OA: closed CC0 ⤵ 10 in-corpus citations
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⚙ AI-generated summary by claude@2026-06, 2026-06-08 ⓘ

This case report details a 48-year-old woman with uterus didelphys and cervical agenesis who presented with abdominal pain, an adnexal mass, elevated CA-125, adenomyosis, a leiomyoma, and ovarian endometriosis.

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Abstract

BACKGROUND: Elevated level of serum CA-125 was detected in a 48-year-old woman who was diagnosed with a lateral fusion defect in association with congenital agenesis of the uterine cervix. This unusual case combined two developmental anomalies of the müllerian duct. CASE REPORT: A 48-year-old woman consulted our outpatient department due to persistent abdominal pain for six months. Bimanual pelvic examination showed absence of the cervix, an anteverted uterus and a 6-cm, left adnexal mass. Ultrasound and computed tomography revealed a uterus didelphys with a 3-cm cystic mass over the right ovary. Serum level of CA-125 was 641.4 U/mL. The patient underwent exploratory laparotomy, and total abdominal hysterectomy with bilateral salpingo-oophorectomy was performed. Pathology confirmed adenomyosis and a leiomyoma of the uterus with functional endometrium in conjunction with endometriosis of the right ovary. CONCLUSION: Multiple müllerian anomalies associated with adenomyosis and endometriosis should be considered in patients presenting with primary amenorrhea. Thorough evaluation, careful planning, fertility preservation and postoperative outcomes should be reviewed.

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Condition tags

mesh:D004715endometriosisadenomyosis

MeSH descriptors

Endometriosis Leiomyoma Ovarian Diseases Uterine Neoplasms Uterus Abdominal Pain Abdominal Pain CA-125 Antigen CA-125 Antigen Cervix Uteri Cervix Uteri Diagnosis, Differential Endometriosis Endometriosis Endometriosis Endometriosis Fallopian Tubes Fallopian Tubes Female Humans

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Cited by (10)

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License: CC0 · commercial use OK